ACY1

aminoacylase 1

Summary

This gene encodes a cytosolic, homodimeric, zinc-binding enzyme that catalyzes the hydrolysis of acylated L-amino acids to L-amino acids and an acyl group, and has been postulated to function in the catabolism and salvage of acylated amino acids. This gene is located on chromosome 3p21.1, a region reduced to homozygosity in small-cell lung cancer (SCLC), and its expression has been reported to be reduced or undetectable in SCLC cell lines and tumors. The amino acid sequence of human aminoacylase-1 is highly homologous to the porcine counterpart, and this enzyme is the first member of a new family of zinc-binding enzymes. Mutations in this gene cause aminoacylase-1 deficiency, a metabolic disorder characterized by central nervous system defects and increased urinary excretion of N-acetylated amino acids. Alternative splicing of this gene results in multiple transcript variants. Read-through transcription also exists between this gene and the upstream ABHD14A (abhydrolase domain containing 14A) gene, as represented in GeneID:100526760. A related pseudogene has been identified on chromosome 18. [provided by RefSeq, Nov 2010]

Known Variants137 total

rsidPosition (GRCh37)AllelesClassClinVar
rs9534204173:52,018,099G/Cuncertain significance
rs3768113503:52,018,116G/Clikely benign
rs2000125123:52,018,128C/Tlikely benign
rs7491676703:52,018,129C/Tuncertain significance
rs10484301253:52,018,130G/Tuncertain significance
rs2008957433:52,018,138C/Guncertain significance
rs340174923:52,018,149C/Glikely benign
rs12571486213:52,018,150A/Guncertain significance
rs1123969053:52,018,184C/Tbenign
rs7454565343:52,018,185G/Auncertain significance
rs15597789463:52,019,212T/Guncertain significance
rs7631194323:52,019,234G/Tuncertain significance
rs7738045753:52,019,255C/Tuncertain significance
rs1997110703:52,019,263G/Cbenign
rs13683074293:52,019,376G/Alikely pathogenic
rs7759076613:52,019,400C/Tlikely benign
rs2022063833:52,019,401G/Clikely benign
rs7749535513:52,019,404T/Clikely benign
rs5477229343:52,019,459C/Tbenign
rs24713861673:52,019,479A/Cuncertain significance
rs3713757773:52,019,883G/Auncertain significance
rs13000426413:52,019,902A/Guncertain significance
rs2010480153:52,019,910G/Cuncertain significance
rs24713879473:52,019,912G/Alikely benign
rs21068327993:52,019,915C/Glikely benign
rs17010383383:52,019,921C/Tlikely benign
rs1395374613:52,019,928A/Guncertain significance
rs1494750493:52,019,935C/Tconflicting classifications of pathogenicity
rs3715657533:52,019,952G/Alikely benign
rs7637932533:52,019,956G/Cuncertain significance
rs24713883733:52,019,973T/Clikely benign
rs6726013303:52,020,270G/Asplice region variantpathogenic
rs17010516833:52,020,271G/Tuncertain significance
rs3763320743:52,020,311C/Tconflicting classifications of pathogenicity
rs21068343883:52,020,326A/Guncertain significance
rs24713902903:52,020,334G/Cuncertain significance
rs15777274723:52,020,347G/Tuncertain significance
rs3238933:52,020,411C/Tbenign
rs7575758743:52,020,412G/Aconflicting classifications of pathogenicity
rs13859045003:52,020,436G/Alikely benign
rs24713910273:52,020,449A/Guncertain significance
rs5727763173:52,020,459G/Auncertain significance
rs5398197373:52,020,460G/Auncertain significance
rs14396970523:52,020,464T/Cuncertain significance
rs7457931353:52,020,468C/Tuncertain significance
rs5532703703:52,020,469G/Auncertain significance
rs7754095083:52,020,475C/Guncertain significance
rs2020981293:52,020,476G/Auncertain significance
rs9423900873:52,020,489C/Tlikely benign
rs2003144953:52,020,515A/Guncertain significance
rs12883331153:52,020,517G/Auncertain significance
rs8875413:52,020,604C/Abenign
rs8875403:52,020,630A/Glikely benign
rs1850864283:52,020,631T/Cbenign
rs7482684683:52,020,665C/Tuncertain significance
rs7608236963:52,020,691T/Alikely benign
rs14073823163:52,020,988C/Tlikely benign
rs1219127003:52,021,009C/Tmissense variantpathogenic
rs15777289833:52,021,017C/Alikely benign
rs21068372873:52,021,044A/Glikely benign
rs1407383683:52,021,045C/Tuncertain significance
rs7729171673:52,021,046G/Auncertain significance
rs7812284303:52,021,081C/Tuncertain significance
rs5548992443:52,021,089C/Tbenign
rs3238943:52,021,092A/Gbenign
rs10046977563:52,021,159A/Clikely benign
rs9927978003:52,021,194G/Auncertain significance
rs12702978813:52,021,198G/Alikely benign
rs1219126993:52,021,204A/Cmissense variantpathogenic
rs1425580423:52,021,222C/Alikely benign
rs17010998333:52,021,227G/Alikely benign
rs2002620333:52,021,308C/Tbenign
rs3238953:52,021,316A/Gbenign
rs17011045783:52,021,318A/Tlikely benign
rs21068384523:52,021,349A/Glikely benign
rs7486023993:52,021,358C/Tlikely benign
rs7805415053:52,021,367C/Tlikely benign
rs2007991863:52,021,394C/Tlikely benign
rs7607897303:52,021,413C/Auncertain significance
rs2017759253:52,021,422A/Gconflicting classifications of pathogenicity
rs7655110743:52,021,428G/Auncertain significance
rs1999473443:52,021,453C/Tuncertain significance
rs7719011063:52,021,454G/Alikely benign
rs14796265893:52,021,456A/Cuncertain significance
rs3730594373:52,021,555C/Tlikely benign
rs7644521143:52,021,556G/Alikely benign
rs7578254363:52,021,565C/Glikely benign
rs2022452443:52,021,590C/Guncertain significance
rs7732114773:52,021,613C/Tlikely benign
rs2015479923:52,021,614G/Alikely benign
rs14892165853:52,021,638C/Tpathogenic
rs8911669423:52,021,644T/Guncertain significance
rs17011228283:52,021,661A/Tuncertain significance
rs10549831963:52,022,535C/Tlikely benign
rs7812221373:52,022,553C/Tuncertain significance
rs10333449013:52,022,579A/Guncertain significance
rs24714010823:52,022,595C/Guncertain significance
rs2006852023:52,022,604G/Auncertain significance
rs9960512313:52,022,609T/Cuncertain significance
rs7678831813:52,022,618A/Tuncertain significance

Showing 100 of 137 variants. Use the SNP search for the full list.

Gene information from NCBI Gene. Variant classifications from ClinVar.