DAW1

dynein assembly factor with WD repeats 1

Summary

Predicted to enable ubiquitin-like ligase-substrate adaptor activity. Predicted to be involved in protein polyubiquitination. Predicted to act upstream of with a positive effect on outer dynein arm assembly. Predicted to act upstream of or within with a positive effect on intraciliary transport. Predicted to act upstream of or within several processes, including cerebrospinal fluid circulation; determination of left/right symmetry; and heart development. Predicted to be located in ciliary basal body. Predicted to be part of SCF ubiquitin ligase complex. Implicated in primary ciliary dyskinesia. [provided by Alliance of Genome Resources, Jul 2025]

Known Variants31 total

rsidPosition (GRCh37)AllelesClassClinVar
rs2016881502:228,736,425T/Cuncertain significance
rs5498837062:228,736,426G/Tbenign
rs11797665902:228,750,094G/Auncertain significance
rs1503474562:228,754,582A/Guncertain significance
rs1930279012:228,754,583G/Cuncertain significance
rs9757482422:228,754,586C/Tuncertain significance
rs1493710812:228,754,609G/Alikely benign
rs7473331722:228,754,655T/Apathogenic
rs7463367062:228,754,681G/Auncertain significance
rs3734532362:228,754,682G/Auncertain significance
rs7626442432:228,754,700C/Tuncertain significance
rs2012779702:228,758,545C/Tuncertain significance
rs21061970582:228,758,550G/Apathogenic
rs10034018172:228,758,587G/Auncertain significance
rs12657745172:228,758,620A/Gpathogenic
rs3726173372:228,758,624A/Guncertain significance
rs1474604752:228,758,626C/Tuncertain significance
rs1463573672:228,767,722G/Tuncertain significance
rs1390696282:228,767,755C/Tuncertain significance
rs9506491472:228,767,770A/Guncertain significance
rs2006402752:228,769,717C/Tuncertain significance
rs1390572802:228,769,729G/Auncertain significance
rs1461214852:228,771,929G/Auncertain significance
rs13656253352:228,771,963C/Guncertain significance
rs7763655952:228,771,966A/Cuncertain significance
rs12578486432:228,783,501G/Auncertain significance
rs16920346312:228,783,507A/Glikely benign
rs5416936332:228,786,155G/Cpathogenic
rs14356873112:228,786,180G/Tpathogenic
rs7805468272:228,786,185C/Tuncertain significance
rs1814123632:228,786,283G/Asplice region variant

Gene information from NCBI Gene. Variant classifications from ClinVar.