ERN1

endoplasmic reticulum to nucleus signaling 1

Summary

This gene encodes the transmembrane protein kinase inositol-requiring enzyme 1. The encoded protein contains two functional catalytic domains, a serine/threonine-protein kinase domain and an endoribonuclease domain. This protein functions as a sensor of unfolded proteins in the endoplasmic reticulum (ER) and triggers an intracellular signaling pathway termed the unfolded protein response (UPR). The UPR is an ER stress response that is conserved from yeast to mammals and activates genes involved in degrading misfolded proteins, regulating protein synthesis and activating molecular chaperones. This protein specifically mediates the splicing and activation of the stress response transcription factor X-box binding protein 1. [provided by RefSeq, Aug 2017]

Known Variants65 total

rsidPosition (GRCh37)AllelesClassClinVar
rs18124930517:62,117,361G/C3 prime UTR variant
rs55103075317:62,121,370G/Tuncertain significance
rs20103218817:62,121,494C/Tuncertain significance
rs54439539217:62,121,503C/Tuncertain significance
rs19965008217:62,121,526C/Tmissense variant
rs36966302817:62,121,527G/Auncertain significance
rs75753029517:62,121,536C/Tuncertain significance
rs6173853817:62,121,544T/Cuncertain significance
rs148014779617:62,122,231T/Cuncertain significance
rs77693005617:62,122,749G/Auncertain significance
rs55190530717:62,122,805C/Tuncertain significance
rs18381999617:62,123,208G/Aintron variant
rs93261252117:62,125,245G/Cuncertain significance
rs75826684717:62,125,271C/Tuncertain significance
rs250942434317:62,125,301C/Auncertain significance
rs6173650817:62,126,458G/Abenign
rs126034326517:62,126,517C/Tuncertain significance
rs122504081317:62,126,529C/Tuncertain significance
rs250942563017:62,126,538C/Auncertain significance
rs76130482417:62,130,142G/Cuncertain significance
rs250942962717:62,130,728C/Tuncertain significance
rs77462533317:62,132,108T/Cuncertain significance
rs36960239217:62,132,174C/Guncertain significance
rs496860717:62,132,330G/C
rs18190000117:62,133,037C/Tlikely benign
rs75437876817:62,133,055G/Alikely benign
rs6173650317:62,133,058G/Cbenign
rs75909951217:62,133,103T/Guncertain significance
rs54636695317:62,133,124G/Auncertain significance
rs75846785517:62,133,144C/Tlikely benign
rs134309038217:62,133,196G/Auncertain significance
rs191292369917:62,135,224T/Guncertain significance
rs129788488917:62,135,251C/Tuncertain significance
rs74562544217:62,135,266G/Auncertain significance
rs37147791317:62,135,281C/Tuncertain significance
rs76939826917:62,135,301C/Tlikely benign
rs75841683517:62,135,344G/Cuncertain significance
rs18529828517:62,137,875C/Tuncertain significance
rs37451874917:62,137,915T/Guncertain significance
rs76714850117:62,137,918T/Cuncertain significance
rs57192825117:62,138,234C/T
rs76492175117:62,141,400C/Tuncertain significance
rs37180236817:62,141,411T/Cuncertain significance
rs134578966817:62,141,418C/Tuncertain significance
rs77094408917:62,141,429G/Auncertain significance
rs155561407117:62,141,433T/Guncertain significance
rs37726577117:62,141,505C/Tuncertain significance
rs75157714417:62,144,056C/Tuncertain significance
rs77356108517:62,144,149G/Auncertain significance
rs19982870217:62,144,271T/Cmissense variant
rs1694743017:62,145,338C/Tregulatory region variant
rs37259382017:62,145,618C/Tuncertain significance
rs37499984417:62,149,423G/Alikely benign
rs94528693017:62,152,584T/Auncertain significance
rs37735151817:62,158,143A/Tuncertain significance
rs650419917:62,160,382C/Aregulatory region variant
rs650420017:62,160,439A/Gregulatory region variant
rs7478059017:62,167,638C/Tintron variant
rs76550189917:62,175,574G/Auncertain significance
rs75854692917:62,175,580C/Tuncertain significance
rs1165589817:62,201,374T/Cintron variant
rs5776753917:62,203,059G/Aintron variant
rs5767662717:62,203,128C/A
rs6027634817:62,203,304C/Tintron variant
rs6104423317:62,206,607T/Aregulatory region variant

Gene information from NCBI Gene. Variant classifications from ClinVar.