FBH1

F-box DNA helicase 1

Summary

This gene encodes a member of the F-box protein family, members of which are characterized by an approximately 40 amino acid motif, the F-box. The F-box proteins constitute one of the four subunits of ubiquitin protein ligase complex called SCFs (SKP1-cullin-F-box), which function in phosphorylation-dependent ubiquitination. The F-box proteins are divided into three classes: Fbws containing WD-40 domains, Fbls containing leucine-rich repeats, and Fbxs containing either different protein-protein interaction modules or no recognizable motifs. The protein encoded by this gene belongs to the Fbx class. It contains an F-box motif and seven conserved helicase motifs, and has both DNA-dependent ATPase and DNA unwinding activities. Alternatively spliced transcript variants encoding distinct isoforms have been identified for this gene. [provided by RefSeq, Jul 2008]

Known Variants62 total

rsidPosition (GRCh37)AllelesClassClinVar
rs75022028310:5,937,076G/Auncertain significance
rs77071407610:5,937,084G/Auncertain significance
rs118247132310:5,937,085G/Auncertain significance
rs74574069110:5,937,103G/Auncertain significance
rs77033447410:5,937,143C/Guncertain significance
rs14255301810:5,944,998G/Auncertain significance
rs253847163410:5,945,022G/Auncertain significance
rs14040552610:5,945,129G/Auncertain significance
rs14955705210:5,945,743A/Gintron variant
rs20204016610:5,948,000G/Auncertain significance
rs140412390110:5,948,009G/Auncertain significance
rs19998216110:5,948,051C/Tuncertain significance
rs253850494210:5,948,053T/Guncertain significance
rs253850632210:5,948,156A/Tuncertain significance
rs13840197210:5,948,170G/Clikely benign
rs14378285410:5,948,174C/Tlikely benign
rs74646650210:5,948,221T/Guncertain significance
rs57812615610:5,948,252C/Guncertain significance
rs76111053710:5,948,279A/Guncertain significance
rs134700375310:5,948,342A/Guncertain significance
rs253850906410:5,948,348G/Auncertain significance
rs14300124410:5,948,356C/Tuncertain significance
rs88791476610:5,948,360T/Cuncertain significance
rs14313595810:5,948,374G/Tuncertain significance
rs78105843410:5,948,387A/Guncertain significance
rs253851021510:5,948,413C/Guncertain significance
rs181384934310:5,948,521C/Tuncertain significance
rs77953690110:5,951,126A/Guncertain significance
rs77622967110:5,951,151G/Auncertain significance
rs37465596010:5,952,926C/Tuncertain significance
rs253856069610:5,952,952G/Cuncertain significance
rs74655834610:5,953,018G/Alikely benign
rs14291003110:5,955,763A/Guncertain significance
rs13984819610:5,956,196G/Cuncertain significance
rs253860276310:5,956,203T/Cuncertain significance
rs253863117710:5,958,198T/Guncertain significance
rs76953492310:5,958,319T/Auncertain significance
rs77583560810:5,959,405G/Auncertain significance
rs253866317510:5,960,346T/Cuncertain significance
rs101652925210:5,960,405C/Auncertain significance
rs77915746310:5,960,424G/Auncertain significance
rs13894620310:5,960,430T/Cuncertain significance
rs19392113810:5,963,227C/Tuncertain significance
rs119812806910:5,963,456G/Auncertain significance
rs20186375310:5,965,620A/Guncertain significance
rs253871250410:5,965,637G/Cuncertain significance
rs75021766210:5,966,298T/Guncertain significance
rs19960511310:5,966,330A/Guncertain significance
rs76927229410:5,966,354G/Auncertain significance
rs14744288910:5,966,355C/Tuncertain significance
rs253872266310:5,966,360G/Auncertain significance
rs253872314310:5,966,412G/Auncertain significance
rs253873393910:5,967,335A/Guncertain significance
rs76475166510:5,967,419C/Tuncertain significance
rs15103240110:5,978,473C/Tuncertain significance
rs253882831410:5,978,480G/Auncertain significance
rs74976208910:5,979,119C/Tuncertain significance
rs76471492610:5,979,172C/Tuncertain significance
rs75410268610:5,979,173G/Alikely benign
rs253883685610:5,979,187A/Cuncertain significance
rs253883694610:5,979,196A/Tuncertain significance
rs77070388110:5,979,235G/Auncertain significance

Gene information from NCBI Gene. Variant classifications from ClinVar.