KLHL3

kelch like family member 3

Summary

This gene is ubiquitously expressed and encodes a full-length protein which has an N-terminal BTB domain followed by a BACK domain and six kelch-like repeats in the C-terminus. These kelch-like repeats promote substrate ubiquitination of bound proteins via interaction of the BTB domain with the CUL3 (cullin 3) component of a cullin-RING E3 ubiquitin ligase (CRL) complex. Muatations in this gene cause pseudohypoaldosteronism type IID (PHA2D); a rare Mendelian syndrome featuring hypertension, hyperkalaemia and metabolic acidosis. Alternative splicing results in multiple transcript variants encoding distinct isoforms. [provided by RefSeq, Mar 2012]

Known Variants259 total

rsidPosition (GRCh37)AllelesClassClinVar
rs10464776125:136,953,349G/Auncertain significance
rs1850103445:136,953,366G/Abenign
rs8860599355:136,953,423T/Cuncertain significance
rs7574026855:136,953,431C/Auncertain significance
rs7685566325:136,953,530T/Cuncertain significance
rs68634145:136,953,577C/Tbenign
rs9350255255:136,953,585C/Guncertain significance
rs9149744145:136,953,602C/Tuncertain significance
rs9464774065:136,953,621A/Guncertain significance
rs9984716555:136,953,707G/Auncertain significance
rs5445199585:136,953,721G/Aconflicting classifications of pathogenicity
rs1427815575:136,953,722G/Alikely benign
rs1506243835:136,953,781G/Alikely benign
rs8860599365:136,953,867A/Cuncertain significance
rs5294625765:136,953,874T/Auncertain significance
rs600669285:136,954,089C/Tbenign
rs8860599375:136,954,314A/Guncertain significance
rs10318364955:136,954,377A/Cuncertain significance
rs8860599405:136,954,516T/Cuncertain significance
rs1455077915:136,954,543C/Abenign
rs14258784785:136,954,581T/Auncertain significance
rs352515125:136,954,582T/Abenign
rs48356845:136,954,583T/Auncertain significance
rs1478013815:136,954,659G/Clikely benign
rs38133145:136,954,719T/Cbenign
rs3734994835:136,954,736C/Tuncertain significance
rs7679314595:136,954,796A/Guncertain significance
rs7531649635:136,954,846C/Tuncertain significance
rs38133155:136,954,861G/Abenign
rs10279884315:136,954,901T/Cuncertain significance
rs1412611175:136,954,982T/Clikely benign
rs5503459845:136,955,024G/Auncertain significance
rs9197934615:136,955,095G/Auncertain significance
rs1862830515:136,955,100G/Alikely benign
rs9386954445:136,955,140G/Auncertain significance
rs5738429785:136,955,302A/Clikely benign
rs8860599445:136,955,315T/Guncertain significance
rs8860599455:136,955,339G/Auncertain significance
rs38133165:136,955,383G/Tbenign
rs5330766895:136,955,427C/Tconflicting classifications of pathogenicity
rs1811204555:136,955,450T/Cuncertain significance
rs1406961465:136,955,520A/Tlikely benign
rs38133175:136,955,539G/Alikely benign
rs8860599465:136,955,619A/Guncertain significance
rs8860599475:136,955,631T/Cuncertain significance
rs1828862725:136,955,699G/Auncertain significance
rs38133185:136,955,707G/Tbenign
rs8860599485:136,955,764C/Guncertain significance
rs11617537275:136,955,868G/Tuncertain significance
rs5349838525:136,955,871C/Tuncertain significance
rs753440155:136,955,891C/Alikely benign
rs17563567325:136,955,941G/Tuncertain significance
rs3751937655:136,956,130C/Tuncertain significance
rs5778340255:136,956,136G/Aconflicting classifications of pathogenicity
rs5540481895:136,956,204G/Aconflicting classifications of pathogenicity
rs1495963815:136,956,336T/Clikely benign
rs8860599495:136,956,353A/Cuncertain significance
rs20576805:136,956,477G/Abenign
rs9620951575:136,956,659T/Guncertain significance
rs12824126665:136,956,663A/Guncertain significance
rs1413939675:136,956,681C/Alikely benign
rs74443705:136,956,683C/Tbenign
rs8860599505:136,956,732T/Cuncertain significance
rs8860599515:136,956,753G/Auncertain significance
rs9257467195:136,956,834T/Cuncertain significance
rs5727653055:136,956,997C/Tconflicting classifications of pathogenicity
rs8860599525:136,957,039A/Guncertain significance
rs17502931515:136,957,106G/Auncertain significance
rs8860599545:136,957,248C/Tuncertain significance
rs8860599555:136,957,286A/Guncertain significance
rs8860599565:136,957,306C/Tuncertain significance
rs5391328955:136,957,488C/Tconflicting classifications of pathogenicity
rs5368070695:136,957,563C/Aconflicting classifications of pathogenicity
rs13787467935:136,957,613G/Cuncertain significance
rs8860599575:136,957,638C/Tuncertain significance
rs1890642905:136,957,646G/Aconflicting classifications of pathogenicity
rs1473058295:136,957,679C/Tlikely benign
rs7627356185:136,957,748C/Tconflicting classifications of pathogenicity
rs24799083075:136,957,804T/Cuncertain significance
rs1438611735:136,957,808G/Alikely benign
rs119502755:136,961,171G/Abenign
rs20743445:136,961,400T/Cbenign
rs20743455:136,961,413G/Abenign
rs24799179635:136,961,426G/Alikely benign
rs17504436135:136,961,452C/Tuncertain significance
rs1994696465:136,961,454G/Amissense variantpathogenic
rs14696007575:136,961,456C/Tuncertain significance
rs3716831965:136,961,471G/Auncertain significance
rs3758716425:136,961,483G/Auncertain significance
rs21498762345:136,961,485C/Tlikely pathogenic
rs1995337405:136,961,504T/Cuncertain significance
rs1994696455:136,961,507T/Cmissense variantpathogenic
rs2014156885:136,961,517C/Tuncertain significance
rs21498762635:136,961,523C/Auncertain significance
rs17504470585:136,961,528T/Guncertain significance
rs10647968645:136,961,552A/Guncertain significance
rs171715255:136,961,566A/Cbenign
rs7492984815:136,961,574C/Tuncertain significance
rs799969495:136,963,746G/Abenign
rs23490085:136,963,757C/Gbenign

Showing 100 of 259 variants. Use the SNP search for the full list.

Gene information from NCBI Gene. Variant classifications from ClinVar.