rs45517412

This is a protein-altering variant in the PKD1 gene.

ClinVar annotation

Pathogenic☆☆☆
16 submitters35 publications

Tuberous sclerosis 2 (TSC2); Tuberous sclerosis syndrome (TSC)

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Research that mentions this SNP (1)

Analysis of 65 tuberous sclerosis complex (TSC) patients byTSC2DGGE,TSC1/TSC2MLPA, andTSC1long-range PCR sequencing, and report of 28 novel mutations
Case reportN=65Nanna D. Rendtorff et al.(2005)· Human Mutation

Analysis of 65 Danish tuberous sclerosis complex (TSC) patients identified pathogenic mutations in 51 patients (78%), including 36 small TSC2 mutations, 4 large TSC2 deletions, and 11 small TSC1 mutations, with 28 novel variants reported. Functional assays confirmed that missense mutations impair tuberin protein function and suppress S6K1 phosphorylation.

Traits studied:Tuberous sclerosis complex

About PKD1

This gene encodes a member of the polycystin protein family. The encoded glycoprotein contains a large N-terminal extracellular region, multiple transmembrane domains and a cytoplasmic C-tail. It is an integral membrane protein that functions as a regulator of calcium permeable cation channels and intracellular calcium homoeostasis. It is also involved in cell-cell/matrix interactions and may modulate G-protein-coupled signal-transduction pathways. It plays a role in renal tubular development, and mutations in this gene cause autosomal dominant polycystic kidney disease type 1 (ADPKD1). ADPKD1 is characterized by the growth of fluid-filled cysts that replace normal renal tissue and result in end-stage renal failure. Splice variants encoding different isoforms have been noted for this gene. Also, six pseudogenes, closely linked in a known duplicated region on chromosome 16p, have been described. [provided by RefSeq, Oct 2008]

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Gene information from NCBI Gene. Variant classifications from ClinVar.

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