CERS3

ceramide synthase 3

Summary

This gene is a member of the ceramide synthase family of genes. The ceramide synthase enzymes regulate sphingolipid synthesis by catalyzing the formation of ceramides from sphingoid base and acyl-coA substrates. This family member is involved in the synthesis of ceramides with ultra-long-chain acyl moieties (ULC-Cers), important to the epidermis in its role in creating a protective barrier from the environment. The protein encoded by this gene has also been implicated in modification of the lipid structures required for spermatogenesis. Mutations in this gene have been associated with male fertility defects, and epidermal defects, including ichthyosis. Alternative splicing results in multiple transcript variants encoding different isoforms. [provided by RefSeq, Aug 2015]

Known Variants84 total

rsidPosition (GRCh37)AllelesClassClinVar
rs102378215:100,942,843G/Tbenign
rs20160237715:100,942,927A/Glikely benign
rs37643780715:100,942,950G/Auncertain significance
rs11542035115:100,942,952C/Tbenign
rs243992815:100,942,962T/Cbenign
rs13789953515:100,942,968C/Tconflicting classifications of pathogenicity
rs14584986115:100,943,043C/Tconflicting classifications of pathogenicity
rs11610167415:100,943,044G/Abenign
rs102378315:100,943,045T/Cbenign
rs254901922715:100,943,047A/Tuncertain significance
rs254901934815:100,943,071C/Tuncertain significance
rs254901960415:100,943,155G/Tuncertain significance
rs54798968915:100,989,218A/G
rs1259284115:100,995,866A/Tbenign
rs1205065515:100,995,925A/Gbenign
rs1259520715:100,996,038C/Tbenign
rs125616495015:100,996,182G/Tlikely pathogenic
rs13994686115:100,996,194G/Abenign
rs76273415615:100,996,202A/Guncertain significance
rs14963795315:100,996,212G/Alikely benign
rs11406553915:100,996,216T/Cbenign
rs201494015:100,996,395G/Abenign
rs1290659215:101,009,249C/Tbenign
rs196604515:101,009,318C/Tbenign
rs1259247815:101,009,381A/Gbenign
rs3410824215:101,009,474A/Tbenign
rs1290973215:101,009,530G/Abenign
rs7404145215:101,009,572G/Cbenign
rs203488852215:101,009,599T/Auncertain significance
rs14679240715:101,009,624G/Alikely benign
rs20092519815:101,009,643G/Tlikely benign
rs37468524715:101,009,669A/Glikely benign
rs7347203915:101,012,926G/Tbenign
rs156677515:101,013,123G/Abenign
rs156764403015:101,013,136C/Tpathogenic
rs11652182415:101,013,153G/Abenign
rs11541159215:101,013,158C/Aconflicting classifications of pathogenicity
rs75223025315:101,013,181C/Tpathogenic
rs75804695115:101,013,182G/Tuncertain significance
rs11555188015:101,013,230G/Abenign
rs106479532815:101,013,233G/Auncertain significance
rs254911639715:101,013,235T/Auncertain significance
rs6203899115:101,016,091G/Abenign
rs19392102015:101,016,284C/Auncertain significance
rs58777699615:101,016,290C/Apathogenic
rs37281436715:101,016,343A/Guncertain significance
rs254911980415:101,016,360C/Tpathogenic
rs117867609615:101,016,370G/Auncertain significance
rs265457415:101,019,529C/Tbenign
rs76355984015:101,019,690G/Alikely benign
rs20000546115:101,019,693G/Abenign
rs1243747415:101,019,793C/Abenign
rs258776315:101,019,819G/Tbenign
rs265457315:101,019,864C/Gbenign
rs265457215:101,020,039C/Tbenign
rs804073715:101,020,065G/Cbenign
rs258776415:101,020,129T/Abenign
rs214226621615:101,020,192A/Clikely pathogenic
rs37288413415:101,020,207G/Auncertain significance
rs265463915:101,023,554G/Cintron variant
rs265463315:101,024,450C/Tbenign
rs1046819115:101,024,681G/Abenign
rs141950816215:101,024,764T/Cuncertain significance
rs56532159515:101,024,831G/Cuncertain significance
rs11559259615:101,024,835C/Tbenign
rs20102546215:101,024,873T/Guncertain significance
rs265462915:101,030,739G/Abenign
rs74791178415:101,031,087G/Alikely pathogenic
rs14813920715:101,031,132C/Tlikely benign
rs150347915:101,031,217C/Tbenign
rs184732315:101,031,442G/Abenign
rs57696998315:101,038,100A/C
rs258777815:101,041,746T/Cbenign
rs254914474615:101,041,873A/Glikely benign
rs19988009015:101,041,894C/Tconflicting classifications of pathogenicity
rs135433215:101,041,896C/Tbenign
rs6040573515:101,041,921T/Cbenign
rs20039119715:101,041,934C/Tlikely benign
rs214232981215:101,041,937A/Guncertain significance
rs14628910215:101,041,964G/Clikely benign
rs76267910215:101,042,012A/Tmissense variantpathogenic
rs20040774515:101,042,029A/Guncertain significance
rs7708945915:101,042,043T/Cbenign
rs8033202315:101,073,444C/Tintron variant

Gene information from NCBI Gene. Variant classifications from ClinVar.