SMCR8

SMCR8-C9orf72 complex subunit

Summary

Enables GTPase activator activity; protein kinase binding activity; and protein kinase inhibitor activity. Contributes to guanyl-nucleotide exchange factor activity. Involved in negative regulation of gene expression; regulation of TOR signaling; and regulation of macroautophagy. Located in Atg1/ULK1 kinase complex; chromatin; and nucleoplasm. Part of guanyl-nucleotide exchange factor complex. [provided by Alliance of Genome Resources, Jul 2025]

Known Variants65 total

rsidPosition (GRCh37)AllelesClassClinVar
rs76992852917:18,219,169T/Auncertain significance
rs254563984417:18,219,195C/Tuncertain significance
rs146918785117:18,219,200C/Guncertain significance
rs119550063517:18,219,240C/Tuncertain significance
rs254563999717:18,219,281A/Cuncertain significance
rs254564003117:18,219,317T/Guncertain significance
rs55562259417:18,219,333A/Guncertain significance
rs37558085117:18,219,416G/Tuncertain significance
rs254564018317:18,219,424T/Clikely benign
rs75415189717:18,219,455G/Tuncertain significance
rs74788339917:18,219,510T/Cuncertain significance
rs37002432517:18,219,538G/Tuncertain significance
rs76213777817:18,219,567T/Cuncertain significance
rs11752128717:18,219,607G/Alikely benign
rs75700984717:18,219,821G/Cuncertain significance
rs139970720517:18,219,839C/Auncertain significance
rs20223245917:18,219,872C/Tuncertain significance
rs20068728917:18,219,879G/Auncertain significance
rs76077039217:18,220,001C/Guncertain significance
rs78027051217:18,220,131A/Guncertain significance
rs54072738717:18,220,176A/Tuncertain significance
rs77320421117:18,220,202A/Guncertain significance
rs254564143417:18,220,262G/Auncertain significance
rs7987584217:18,220,268A/Gbenign
rs74929284017:18,220,271C/Tuncertain significance
rs122852624717:18,220,299C/Tuncertain significance
rs14550698117:18,220,450C/Guncertain significance
rs37455817117:18,220,575C/Tuncertain significance
rs75150736417:18,220,586G/Auncertain significance
rs75346079217:18,220,614G/Auncertain significance
rs74854736917:18,220,643G/Auncertain significance
rs57329889117:18,220,652A/Tuncertain significance
rs54476508617:18,220,697G/Tuncertain significance
rs156775865017:18,220,701T/Cuncertain significance
rs198235113117:18,220,715C/Tuncertain significance
rs14730806217:18,220,774C/Auncertain significance
rs76602454817:18,220,791C/Tuncertain significance
rs55151132317:18,220,814G/Auncertain significance
rs37095843117:18,220,905C/Auncertain significance
rs254564227317:18,220,930T/Guncertain significance
rs75184013317:18,220,956G/Auncertain significance
rs36981838617:18,221,022G/Alikely benign
rs77610107417:18,221,112A/Guncertain significance
rs37034091217:18,221,127C/Tuncertain significance
rs78078563217:18,221,190G/Cuncertain significance
rs13789008517:18,221,201G/Auncertain significance
rs53867768517:18,221,317A/Cuncertain significance
rs254564274217:18,221,354G/Cuncertain significance
rs13965170217:18,221,399C/Tuncertain significance
rs137865968617:18,221,403G/Tuncertain significance
rs74940210017:18,221,418T/Cuncertain significance
rs77090972517:18,221,423A/Guncertain significance
rs722180717:18,221,799T/G
rs75308219017:18,225,935G/Cuncertain significance
rs93642348117:18,225,965G/Auncertain significance
rs36846235517:18,225,974C/Tuncertain significance
rs76256019517:18,225,975G/Auncertain significance
rs20163893517:18,225,983C/Tuncertain significance
rs20166479517:18,226,056G/Auncertain significance
rs37318312317:18,226,070C/Tuncertain significance
rs20034093517:18,226,071G/Auncertain significance
rs76652611617:18,226,152A/Cuncertain significance
rs20208013717:18,226,187G/Auncertain significance
rs1294911917:18,229,452T/Adownstream gene variant
rs94145417:18,230,380T/G

Gene information from NCBI Gene. Variant classifications from ClinVar.