GMDS

GDP-mannose 4,6-dehydratase

Summary

GDP-mannose 4,6-dehydratase (GMD; EC 4.2.1.47) catalyzes the conversion of GDP-mannose to GDP-4-keto-6-deoxymannose, the first step in the synthesis of GDP-fucose from GDP-mannose, using NADP+ as a cofactor. The second and third steps of the pathway are catalyzed by a single enzyme, GDP-keto-6-deoxymannose 3,5-epimerase, 4-reductase, designated FX in humans (MIM 137020).[supplied by OMIM, Aug 2009]

Known Variants40 total

rsidPosition (GRCh37)AllelesClassClinVar
rs24805300666:1,624,425C/Tuncertain significance
rs1498199716:1,624,436C/Tuncertain significance
rs348267106:1,666,657C/Tintron variant
rs112427136:1,668,142G/T
rs28148146:1,678,538C/Aregulatory region variant
rs122030576:1,687,710C/Tintron variant
rs69368816:1,713,692C/Tintron variant
rs8882403136:1,742,718T/Cuncertain significance
rs1431048346:1,742,788C/Tlikely benign
rs7492767766:1,742,789G/Auncertain significance
rs69167606:1,747,021C/Tintron variant
rs65968486:1,749,782A/Gintron variant
rs38001206:1,894,146G/A
rs77622916:1,912,462C/Tintron variant
rs38001316:1,918,262A/T
rs126645876:1,948,703A/Tintron variant
rs27612356:1,951,135C/Tintron variant
rs623916326:1,958,002G/Tintron variant
rs25333732196:1,960,190T/Cuncertain significance
rs25333827056:1,961,157A/Guncertain significance
rs7746255106:1,961,172G/Auncertain significance
rs14623673016:1,961,184G/Auncertain significance
rs562261946:1,963,754T/Cintron variant
rs121755316:1,966,966C/Tintron variant
rs171345496:1,974,874T/Aintron variant
rs560311926:1,980,208T/Aintron variant
rs93923486:1,989,604G/Aintron variant
rs77712476:2,005,591A/G
rs69122556:2,047,772C/Gintron variant
rs1159862976:2,050,791A/C
rs112427356:2,055,677G/T
rs93923656:2,091,975A/G
rs93786826:2,094,123T/A
rs69140866:2,096,035T/Cintron variant
rs3694925116:2,117,711A/Guncertain significance
rs7716503356:2,117,772G/Auncertain significance
rs13911413926:2,117,775G/Auncertain significance
rs11963886:2,232,808T/Gregulatory region variant
rs93786886:2,235,633G/Aintron variant
rs7610304096:2,245,631G/Auncertain significance

Gene information from NCBI Gene. Variant classifications from ClinVar.