WFS1

wolframin ER transmembrane glycoprotein

Summary

This gene encodes a transmembrane protein, which is located primarily in the endoplasmic reticulum and ubiquitously expressed with highest levels in brain, pancreas, heart, and insulinoma beta-cell lines. Mutations in this gene are associated with Wolfram syndrome, also called DIDMOAD (Diabetes Insipidus, Diabetes Mellitus, Optic Atrophy, and Deafness), an autosomal recessive disorder. The disease affects the brain and central nervous system. Mutations in this gene can also cause autosomal dominant deafness 6 (DFNA6), also known as DFNA14 or DFNA38. Alternatively spliced transcript variants have been found for this gene. [provided by RefSeq, Mar 2009]

Known Variants1,333 total

rsidPosition (GRCh37)AllelesClassClinVar
rs46893884:6,270,056G/Aupstream gene variant
rs43202004:6,271,043A/C
rs131078064:6,271,071T/A
rs131274454:6,271,150C/A
rs42735454:6,271,416G/Tregulatory region variantbenign
rs715376834:6,271,483A/Glikely benign
rs17297431994:6,271,563T/Alikely benign
rs24741476304:6,271,575T/Alikely benign
rs5429770174:6,271,599G/Tconflicting classifications of pathogenicity
rs3732875224:6,271,606A/Gconflicting classifications of pathogenicity
rs8860595214:6,271,614G/Tconflicting classifications of pathogenicity
rs5762846304:6,271,617C/Tconflicting classifications of pathogenicity
rs8860595224:6,271,618A/Gconflicting classifications of pathogenicity
rs5421167474:6,271,620A/Gconflicting classifications of pathogenicity
rs8683291844:6,271,641A/Gconflicting classifications of pathogenicity
rs8860595234:6,271,642T/Gconflicting classifications of pathogenicity
rs8860595244:6,271,647C/Guncertain significance
rs17297491534:6,271,654G/Cconflicting classifications of pathogenicity
rs8860595254:6,271,692C/Guncertain significance
rs15785795014:6,271,704G/Cconflicting classifications of pathogenicity
rs5278689284:6,271,720C/Tlikely benign
rs5479986674:6,271,752C/Tlikely benign
rs10251461944:6,271,755C/Abenign
rs68307654:6,271,826C/Tbenign
rs5489903114:6,271,970G/Cbenign
rs799448604:6,273,565G/Cuncertain significance
rs789378054:6,277,769G/Tuncertain significance
rs792714404:6,278,923G/Cbenign
rs1127702954:6,278,973G/Cbenign
rs1855728734:6,279,044T/Clikely benign
rs109377144:6,279,047T/Cbenign
rs7463406274:6,279,179C/Tconflicting classifications of pathogenicity
rs715243634:6,279,191C/Tbenign
rs14327040194:6,279,201C/Tuncertain significance
rs1381654864:6,279,202C/Tuncertain significance
rs3729288104:6,279,203G/Tlikely benign
rs7602566494:6,279,210C/Tconflicting classifications of pathogenicity
rs12094021444:6,279,211C/Tuncertain significance
rs11855908274:6,279,215C/Alikely benign
rs1426514464:6,279,223A/Glikely benign
rs24741573154:6,279,226C/Auncertain significance
rs7594352824:6,279,227C/Tlikely benign
rs346538054:6,279,229C/Tuncertain significance
rs7650033574:6,279,230G/Alikely benign
rs3763352164:6,279,238C/Tconflicting classifications of pathogenicity
rs12823942414:6,279,239G/Alikely benign
rs14170206944:6,279,240C/Tpathogenic
rs7574476314:6,279,243C/Guncertain significance
rs21091079234:6,279,249G/Tuncertain significance
rs10401065574:6,279,250C/Tuncertain significance
rs7508592804:6,279,251G/Alikely benign
rs7566674624:6,279,252C/Tuncertain significance
rs715243644:6,279,253G/Auncertain significance
rs7476585234:6,279,258C/Tpathogenic
rs5518674774:6,279,259G/Auncertain significance
rs7771689564:6,279,263C/Tuncertain significance
rs3975171984:6,279,265A/Guncertain significance
rs5509757294:6,279,274C/Gconflicting classifications of pathogenicity
rs7275047304:6,279,277C/Tuncertain significance
rs715396604:6,279,278G/Alikely benign
rs12506937984:6,279,286A/Guncertain significance
rs14103663974:6,279,287G/Tuncertain significance
rs13487364204:6,279,290G/Alikely benign
rs12254069564:6,279,292G/Cuncertain significance
rs7753428004:6,279,295G/Auncertain significance
rs5315939024:6,279,296C/Tconflicting classifications of pathogenicity
rs7743304854:6,279,297G/Tlikely pathogenic
rs14835621694:6,279,304C/Tuncertain significance
rs715309234:6,279,306C/Tstop gainedpathogenic
rs7508061514:6,279,307G/Aconflicting classifications of pathogenicity
rs11795837244:6,279,309G/Auncertain significance
rs7275037464:6,279,310C/Tconflicting classifications of pathogenicity
rs5668767934:6,279,311A/Tlikely benign
rs7668614574:6,279,312C/Auncertain significance
rs7543468934:6,279,314C/Tconflicting classifications of pathogenicity
rs10148922174:6,279,315G/Auncertain significance
rs7773064774:6,279,318C/Tuncertain significance
rs14301138844:6,279,320C/Tlikely benign
rs17300359774:6,279,322A/Guncertain significance
rs3975171954:6,279,325C/Tconflicting classifications of pathogenicity
rs1117733404:6,279,336C/Aconflicting classifications of pathogenicity
rs13242726934:6,279,339G/Cuncertain significance
rs21091080454:6,279,340G/Tuncertain significance
rs21091080484:6,279,346G/Auncertain significance
rs12720943094:6,279,348G/Auncertain significance
rs1125981704:6,279,350C/Tconflicting classifications of pathogenicity
rs3727833924:6,279,351G/Tconflicting classifications of pathogenicity
rs10575248874:6,279,354G/Aconflicting classifications of pathogenicity
rs3696718904:6,279,355C/Tconflicting classifications of pathogenicity
rs13622031594:6,279,356G/Alikely benign
rs8675121864:6,279,357G/Tuncertain significance
rs715243654:6,279,358C/Tuncertain significance
rs14504993224:6,279,362C/Tlikely benign
rs7685204524:6,279,363G/Auncertain significance
rs7618583834:6,279,374G/Alikely benign
rs17300389224:6,279,382A/Cuncertain significance
rs7677773664:6,279,385C/Tuncertain significance
rs13156733484:6,279,386C/Alikely benign
rs7735025134:6,279,393C/Tuncertain significance
rs5370048394:6,279,394G/Auncertain significance

Showing 100 of 1,333 variants. Use the SNP search for the full list.

Gene information from NCBI Gene. Variant classifications from ClinVar.